Ontology-based expansion of virtual gene panels to improve diagnostic efficiency for rare genetic diseases.

Journal: BMC medical informatics and decision making
PMID:

Abstract

BACKGROUND: Virtual Gene Panels (VGP) comprising disease-associated causal genes are utilized in the diagnosis of rare genetic diseases to evaluate candidate genes identified by whole-genome and whole-exome sequencing. VGPs generated by the PanelApp software were utilized in a UK 100,000 Genome Project pilot study to filter candidate genes, thus enhancing diagnostic efficiency for rare diseases. However, PanelApp also filtered out disease-causing genes in nearly 50% of the cases.

Authors

  • Jaemoon Shin
    Database Center for Life Science, Kashiwa, Chiba, Japan.
  • Toyofumi Fujiwara
    Database Center for Life Science, Kashiwa, Chiba, Japan.
  • Hirotomo Saitsu
    Hamamatsu University School of Medicine, Hamamatsu, Japan.
  • Atsuko Yamaguchi
    Database Center for Life Science, Research Organization of Information and Systems, Kashiwa, Japan.