CADD-Splice-improving genome-wide variant effect prediction using deep learning-derived splice scores.

Journal: Genome medicine
PMID:

Abstract

BACKGROUND: Splicing of genomic exons into mRNAs is a critical prerequisite for the accurate synthesis of human proteins. Genetic variants impacting splicing underlie a substantial proportion of genetic disease, but are challenging to identify beyond those occurring at donor and acceptor dinucleotides. To address this, various methods aim to predict variant effects on splicing. Recently, deep neural networks (DNNs) have been shown to achieve better results in predicting splice variants than other strategies.

Authors

  • Philipp Rentzsch
    Charité - Universitätsmedizin Berlin, 10117, Berlin, Germany.
  • Max Schubach
    Institute for Medical and Human Genetics, Charité - Universitätsmedizin Berlin, Augustenburger Platz 1, 13353, Berlin, Germany.
  • Jay Shendure
    Department of Genome Sciences, University of Washington, Seattle, WA, 98109, USA.
  • Martin Kircher
    Charité - Universitätsmedizin Berlin, 10117, Berlin, Germany. martin.kircher@bihealth.de.